TY - JOUR
T1 - Survival and predictors of death among primary immunodeficient patients
T2 - A registry-based study
AU - Al-Herz, Waleed
AU - Moussa, Mohamed A.A.
N1 - Funding Information:
Kuwait National Primary Immunodeficiency Disorders Registry (KNPIDR) This Registry was established to create a database for organizing epidemiological studies and clinical research about PID in Kuwait [5]. The registry was approved through a research project by the Human Subjects Research and Ethics Committee of the Ministry of Health, Kuwait. Patients were diagnosed and classified according to the clinical and laboratory criteria of PID reported by the IUIS Primary Immunodeficiency Diseases Classification Committee [6]. Secondary immunodeficiencies (drug-induced, virus-induced, and immunodeficiency associated with metabolic disorders, etc.) were ruled out by obtaining detailed history and by performing appropriate testing when these disorders were suspected.
Funding Information:
Acknowledgment The Kuwait National Primary Immunodeficiency Registry (KNPIDR) was established by a fund from the Kuwait Foundation for the Advancement of Science (KFAS).
PY - 2012/6
Y1 - 2012/6
N2 - Purposes: The aims of this study were to investigate survival among patients with primary immunodeficiency disorders (PID) in Kuwait and to determine whether certain variables were associated with increased risk of death. Methods: The data of 176 patients (98 males and 78 females) were extracted from the Kuwait National Primary Immunodeficiency Disorders Registry and the observation period was from January 2004 to July 2011. Results: The distribution of the reported patients was combined T- and B-cell immunodeficiencies (30.1%), predominantly antibody immunodeficiency (19.9%), other well-defined immunodeficiencies (25%), diseases of immune dysregulation (14.8%), congenital defects of phagocyte number, function or both (6.25%), and complement deficiencies (4.0%). In a total of 619.1 patient-years at risk, 48 patients died (mortality incidence rate 77.53 per 1,000 person-years). The overall survival in the studied cohort was 72.7% (72.4% for males and 73.1% for females). The most common cause of death was sepsis (46%) followed by pneumonia (29%). The probabilities that a patient survived 2, 4, and 6 years after onset of symptoms were 76%, 73%, and 69%, respectively. The variables that were found to be predictors for death are parental consanguinity, sepsis, adenovirus and CMV infections, failure to thrive, PID category, and onset age <6 months. Conclusions: Patients with PID have decreased probabilities of survival that are variable between PID categories. Early diagnosis and aggressive therapeutic interventions specifically of patients with history of the variables associated with increased risk of death may help increase their chance of survival.
AB - Purposes: The aims of this study were to investigate survival among patients with primary immunodeficiency disorders (PID) in Kuwait and to determine whether certain variables were associated with increased risk of death. Methods: The data of 176 patients (98 males and 78 females) were extracted from the Kuwait National Primary Immunodeficiency Disorders Registry and the observation period was from January 2004 to July 2011. Results: The distribution of the reported patients was combined T- and B-cell immunodeficiencies (30.1%), predominantly antibody immunodeficiency (19.9%), other well-defined immunodeficiencies (25%), diseases of immune dysregulation (14.8%), congenital defects of phagocyte number, function or both (6.25%), and complement deficiencies (4.0%). In a total of 619.1 patient-years at risk, 48 patients died (mortality incidence rate 77.53 per 1,000 person-years). The overall survival in the studied cohort was 72.7% (72.4% for males and 73.1% for females). The most common cause of death was sepsis (46%) followed by pneumonia (29%). The probabilities that a patient survived 2, 4, and 6 years after onset of symptoms were 76%, 73%, and 69%, respectively. The variables that were found to be predictors for death are parental consanguinity, sepsis, adenovirus and CMV infections, failure to thrive, PID category, and onset age <6 months. Conclusions: Patients with PID have decreased probabilities of survival that are variable between PID categories. Early diagnosis and aggressive therapeutic interventions specifically of patients with history of the variables associated with increased risk of death may help increase their chance of survival.
KW - Primary immunodeficiency
KW - consanguinity
KW - death
KW - failure to thrive
KW - registry
KW - survival
UR - https://www.scopus.com/pages/publications/84861481569
U2 - 10.1007/s10875-011-9636-1
DO - 10.1007/s10875-011-9636-1
M3 - Article
C2 - 22205205
AN - SCOPUS:84861481569
SN - 0271-9142
VL - 32
SP - 467
EP - 473
JO - Journal of Clinical Immunology
JF - Journal of Clinical Immunology
IS - 3
ER -